Javascript must be enabled to continue!
Identification of Two Novel Pathogenic Variants of the ATM Gene in the Iranian-Azeri Turkish Ethnic Group by Applying Whole Exome Sequencing
View through CrossRef
Background:
The ATM gene encodes a multifunctional kinase involved in important
cellular functions, such as checkpoint signaling and apoptosis, in response to DNA damage. Bi-allelic
pathogenic variants in this gene cause Ataxia Telangiectasia (AT), while carriers of ATM
pathogenic variants are at increased risk of cancer depending on the pathogenicity of the variant
they carry. Identifying pathogenic variants can aid in the management of the disease in carriers.
Methods:
Whole-exome sequencing (WES) was performed on three unrelated patients from the
Iranian-Azeri Turkish ethnic group referred to a genetic center for analysis. WES was also conducted
on 400 individuals from the same ethnic group to determine the frequencies of all ATM
variants. Blood samples were collected from the patients and their family members for DNA extraction,
and PCR-Sanger sequencing was performed to confirm the WES results.
Results:
The first proband with AT disease had two novel compound heterozygote variants
(c.2639-2A>T, c.8708delC) in the ATM gene revealed by WES analysis, which was potentially/-
likely pathogenic. The second proband with bi-lateral breast cancer had a homozygous pathogenic
variant (c.6067G>A) in the ATM gene identified by WES analysis. The third case with a family
history of cancer had a heterozygous synonymous pathogenic variant (c.7788G>A) in the ATM
gene found by WES analysis. Sanger sequencing confirmed the WES results, and bioinformatics
analysis of the mutated ATM RNA and protein structure added evidence for the potential pathogenicity
of the novel variants. WES analysis of the cohort revealed 38 different variants, including
a variant (rs1800057, ATM:c.3161C>G, p.P1054R) associated with prostate cancer that had a higher
frequency in our cohort.
Conclusion:
Genetic analysis of three unrelated families with ATM-related disorders discovered
two novel pathogenic variants. A homozygous missense pathogenic variant was identified in a woman
with bi-lateral breast cancer, and a synonymous but pathogenic variant was found in a family
with a history of different cancers.
Bentham Science Publishers Ltd.
Title: Identification of Two Novel Pathogenic Variants of the ATM Gene in
the Iranian-Azeri Turkish Ethnic Group by Applying Whole Exome
Sequencing
Description:
Background:
The ATM gene encodes a multifunctional kinase involved in important
cellular functions, such as checkpoint signaling and apoptosis, in response to DNA damage.
Bi-allelic
pathogenic variants in this gene cause Ataxia Telangiectasia (AT), while carriers of ATM
pathogenic variants are at increased risk of cancer depending on the pathogenicity of the variant
they carry.
Identifying pathogenic variants can aid in the management of the disease in carriers.
Methods:
Whole-exome sequencing (WES) was performed on three unrelated patients from the
Iranian-Azeri Turkish ethnic group referred to a genetic center for analysis.
WES was also conducted
on 400 individuals from the same ethnic group to determine the frequencies of all ATM
variants.
Blood samples were collected from the patients and their family members for DNA extraction,
and PCR-Sanger sequencing was performed to confirm the WES results.
Results:
The first proband with AT disease had two novel compound heterozygote variants
(c.
2639-2A>T, c.
8708delC) in the ATM gene revealed by WES analysis, which was potentially/-
likely pathogenic.
The second proband with bi-lateral breast cancer had a homozygous pathogenic
variant (c.
6067G>A) in the ATM gene identified by WES analysis.
The third case with a family
history of cancer had a heterozygous synonymous pathogenic variant (c.
7788G>A) in the ATM
gene found by WES analysis.
Sanger sequencing confirmed the WES results, and bioinformatics
analysis of the mutated ATM RNA and protein structure added evidence for the potential pathogenicity
of the novel variants.
WES analysis of the cohort revealed 38 different variants, including
a variant (rs1800057, ATM:c.
3161C>G, p.
P1054R) associated with prostate cancer that had a higher
frequency in our cohort.
Conclusion:
Genetic analysis of three unrelated families with ATM-related disorders discovered
two novel pathogenic variants.
A homozygous missense pathogenic variant was identified in a woman
with bi-lateral breast cancer, and a synonymous but pathogenic variant was found in a family
with a history of different cancers.
Related Results
Whole Exome Sequencing and Extended Thrombophilia Testing in Patients with Venous Thromboembolism
Whole Exome Sequencing and Extended Thrombophilia Testing in Patients with Venous Thromboembolism
Abstract
Introduction: Venous thromboembolism (VTE), defined as deep venous thrombosis (DVT) and pulmonary embolism (PE), is a cause of significant morbidity and mor...
Abstract 1345: ATM kinase activity is dispensable in mitochondrial autophagy
Abstract 1345: ATM kinase activity is dispensable in mitochondrial autophagy
Abstract
Ataxia telangiectasia mutated (ATM), a critical DNA damage sensor with protein kinase activity, is frequently deleted or mutated in human cancers including ...
ATM dysfunction across ataxia telangiectasia and leukemias: A systematic review of genetic drivers and functional impact
ATM dysfunction across ataxia telangiectasia and leukemias: A systematic review of genetic drivers and functional impact
Abstract
Introduction Ataxia-telangiectasia (AT) is a rare autosomal recessive disorder caused by mutations in the ATM g...
Clinical Implications of Germline Predisposition Gene Variants in Patients with Refractory or Relapsed B Acute Lymphoblastic Leukemia
Clinical Implications of Germline Predisposition Gene Variants in Patients with Refractory or Relapsed B Acute Lymphoblastic Leukemia
Objectives:Gene variants are important factors in prognosis of the patients with hematological malignancies. In current study, our team investigate the relationship between blood a...
Ataxia-Telangiectasia Mutated Gene Controls Insulin-Like Growth Factor I Receptor Gene Expression in a Deoxyribonucleic Acid Damage Response Pathway via Mechanisms Involving Zinc-Finger Transcription Factors Sp1 and WT1
Ataxia-Telangiectasia Mutated Gene Controls Insulin-Like Growth Factor I Receptor Gene Expression in a Deoxyribonucleic Acid Damage Response Pathway via Mechanisms Involving Zinc-Finger Transcription Factors Sp1 and WT1
AbstractThe IGF-I receptor (IGF-IR) has a central role in cell cycle progression as well as in the establishment of the transformed phenotype. Increased expression of the IGF-IR ge...
Maximising Value of Gas Tracer Surveillance via Simulation
Maximising Value of Gas Tracer Surveillance via Simulation
Abstract
Tracer surveillance is an important part of the integrated field surveillance programme. It becomes an increasingly important tool in evaluation of reser...
Clinicopathologic features and prognosis of breast cancer in germline
ATM
and
CHEK2
carriers: A monocentric retrospective study.
Clinicopathologic features and prognosis of breast cancer in germline
ATM
and
CHEK2
carriers: A monocentric retrospective study.
e22625
Background:
Germline pathogenic or likely pathogenic variants (PV/LPVs) in moderate-risk genes ...
Abstract 2379: Elaborating the mechanism of PARP synthetic lethality in ATM loss
Abstract 2379: Elaborating the mechanism of PARP synthetic lethality in ATM loss
Abstract
PARP inhibitors have transformed the treatment for ovarian cancer, which is known to have high incidence of homologous recombination (HR) deficiency through...

